TY - JOUR
T1 - ADAM10 is indispensable for longitudinal bone growth in mice
AU - Mizuno, Sakiko
AU - Yoda, Masaki
AU - Kimura, Tokuhiro
AU - Shimoda, Masayuki
AU - Akiyama, Haruhiko
AU - Chiba, Kazuhiro
AU - Nakamura, Masaya
AU - Horiuchi, Keisuke
N1 - Funding Information:
We would like to thank Mika Imamura and Yuri Suzuki for their technical support. This work was supported in part by JSPS KAKENHI (Grant Number 24390358 and 19 K09636 (to KH)).
Publisher Copyright:
© 2020
PY - 2020/5
Y1 - 2020/5
N2 - Skeletal development is a highly sophisticated process in which the expression of a variety of growth factors, signaling molecules, and extracellular matrix proteins is spatially and temporally orchestrated. In the present study, we show that ADAM10, a transmembrane protease that is critically involved in the functional regulation of various membrane-bound molecules, plays an essential role in the longitudinal growth of long bones and in skeletal development. We found that mutant mice lacking ADAM10 in osteochondroprogenitors exhibited marked growth retardation and had shorter long bones than the control mice. Histomorphometric analysis revealed that the mutant mice had a shorter hypertrophic zone and that their hypertrophic chondrocytes were smaller in size than those of the control mice. Unexpectedly, we found that the mRNA expression of the chemokine CXCL12 and its receptor CXCR4 were significantly reduced in cartilage tissues lacking ADAM10. Further, exogenous supplementation of recombinant CXCL12 rescued the defect in the ADAM10-deficient growth plate in an ex vivo culture model. Taken together, our data show a previously unknown role for ADAM10 in skeletal development that involves its regulation of the CXCL12 and CXCR4 signaling pathway.
AB - Skeletal development is a highly sophisticated process in which the expression of a variety of growth factors, signaling molecules, and extracellular matrix proteins is spatially and temporally orchestrated. In the present study, we show that ADAM10, a transmembrane protease that is critically involved in the functional regulation of various membrane-bound molecules, plays an essential role in the longitudinal growth of long bones and in skeletal development. We found that mutant mice lacking ADAM10 in osteochondroprogenitors exhibited marked growth retardation and had shorter long bones than the control mice. Histomorphometric analysis revealed that the mutant mice had a shorter hypertrophic zone and that their hypertrophic chondrocytes were smaller in size than those of the control mice. Unexpectedly, we found that the mRNA expression of the chemokine CXCL12 and its receptor CXCR4 were significantly reduced in cartilage tissues lacking ADAM10. Further, exogenous supplementation of recombinant CXCL12 rescued the defect in the ADAM10-deficient growth plate in an ex vivo culture model. Taken together, our data show a previously unknown role for ADAM10 in skeletal development that involves its regulation of the CXCL12 and CXCR4 signaling pathway.
KW - ADAM10
KW - CXCL12
KW - Hypertrophic chondrocyte
KW - Skeletal development
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U2 - 10.1016/j.bone.2020.115273
DO - 10.1016/j.bone.2020.115273
M3 - Article
C2 - 32062003
AN - SCOPUS:85079685010
SN - 8756-3282
VL - 134
JO - Bone
JF - Bone
M1 - 115273
ER -