TY - JOUR
T1 - Identification of the genetic and clinical characteristics of neuroblastomas using genome-wide analysis
AU - Uryu, Kumiko
AU - Nishimura, Riki
AU - Kataoka, Keisuke
AU - Sato, Yusuke
AU - Nakazawa, Atsuko
AU - Suzuki, Hiromichi
AU - Yoshida, Kenichi
AU - Seki, Masafumi
AU - Hiwatari, Mitsuteru
AU - Isobe, Tomoya
AU - Shiraishi, Yuichi
AU - Chiba, Kenichi
AU - Tanaka, Hiroko
AU - Miyano, Satoru
AU - Koh, Katsuyoshi
AU - Hanada, Ryoji
AU - Oka, Akira
AU - Hayashi, Yasuhide
AU - Ohira, Miki
AU - Kamijo, Takehiko
AU - Nagase, Hiroki
AU - Takimoto, Tetsuya
AU - Tajiri, Tatsuro
AU - Nakagawara, Akira
AU - Ogawa, Seishi
AU - Takita, Junko
N1 - Funding Information:
This work was supported by KAKENHI (17H04224 and 26293242) of Japan Society of Promotion of Science; Research on Measures for Intractable Diseases, Health, and Labor Sciences Research Grants, Ministry of Health, Labor and Welfare and by The Project for Development of Innovative Research on Cancer Therapeutics (P-DIRECT) and P-CREATE.
Publisher Copyright:
© Uryu et al.
PY - 2017
Y1 - 2017
N2 - To provide better insight into the genetic signatures of neuroblastomas, we analyzed 500 neuroblastomas (included specimens from JNBSG) using targeteddeep sequencing for 10 neuroblastoma-related genes and SNP arrays analysis. ALK expression was evaluated using immunohistochemical analysis in 259 samples. Based on genetic alterations, the following 6 subgroups were identified: groups A (ALK abnormalities), B (other gene mutations), C (MYCN amplification), D (11q loss of heterozygosity [LOH]), E (at least 1 copy number variants), and F (no genetic changes). Groups A to D showed advanced disease and poor prognosis, whereas groups E and F showed excellent prognosis. Intriguingly, in group A, MYCN amplification was not a significant prognostic marker, while high ALK expression was a relevant indicator for prognosis (P = 0.033). Notably, the co-existence of MYCN amplification and 1p LOH, and the co-deletion of 3p and 11q were significant predictors of relapse (P = 0.043 and P = 0.040). Additionally, 6q/8p LOH and 17q gain were promising indicators of survival in patients older than 5 years, and 1p, 4p, and 11q LOH potentially contributed to outcome prediction in the intermediate-risk group. Our genetic overview clarifies the clinical impact of genetic signatures and aids in the better understanding of genetic basis of neuroblastoma.
AB - To provide better insight into the genetic signatures of neuroblastomas, we analyzed 500 neuroblastomas (included specimens from JNBSG) using targeteddeep sequencing for 10 neuroblastoma-related genes and SNP arrays analysis. ALK expression was evaluated using immunohistochemical analysis in 259 samples. Based on genetic alterations, the following 6 subgroups were identified: groups A (ALK abnormalities), B (other gene mutations), C (MYCN amplification), D (11q loss of heterozygosity [LOH]), E (at least 1 copy number variants), and F (no genetic changes). Groups A to D showed advanced disease and poor prognosis, whereas groups E and F showed excellent prognosis. Intriguingly, in group A, MYCN amplification was not a significant prognostic marker, while high ALK expression was a relevant indicator for prognosis (P = 0.033). Notably, the co-existence of MYCN amplification and 1p LOH, and the co-deletion of 3p and 11q were significant predictors of relapse (P = 0.043 and P = 0.040). Additionally, 6q/8p LOH and 17q gain were promising indicators of survival in patients older than 5 years, and 1p, 4p, and 11q LOH potentially contributed to outcome prediction in the intermediate-risk group. Our genetic overview clarifies the clinical impact of genetic signatures and aids in the better understanding of genetic basis of neuroblastoma.
KW - ALK
KW - ALK immunohistochemistry staining
KW - Copy number variants
KW - Japan neuroblastoma study group (JNBSG)
KW - Target amplicon deep sequencing
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U2 - 10.18632/oncotarget.22495
DO - 10.18632/oncotarget.22495
M3 - Article
C2 - 29296183
AN - SCOPUS:85037379224
SN - 1949-2553
VL - 8
SP - 107513
EP - 107529
JO - Oncotarget
JF - Oncotarget
IS - 64
ER -