TY - JOUR
T1 - Multimodal analyses of a non-human primate model harboring mutant amyloid precursor protein transgenes driven by the human EF1α promoter.
AU - Yoshimatsu, Sho
AU - Seki, Fumiko
AU - Okahara, Junko
AU - Watanabe, Hirotaka
AU - Sasaguri, Hiroki
AU - Haga, Yawara
AU - Hata, Jun ichi
AU - Sanosaka, Tsukasa
AU - Inoue, Takashi
AU - Mineshige, Takayuki
AU - Lee, Chia Ying
AU - Shinohara, Haruka
AU - Kurotaki, Yoko
AU - Komaki, Yuji
AU - Kishi, Noriyuki
AU - Murayama, Ayaka Y.
AU - Nagai, Yuji
AU - Minamimoto, Takafumi
AU - Yamamoto, Masafumi
AU - Nakajima, Mayutaka
AU - Zhou, Zhi
AU - Nemoto, Akisa
AU - Sato, Tsukika
AU - Ikeuchi, Takeshi
AU - Sahara, Naruhiko
AU - Morimoto, Satoru
AU - Shiozawa, Seiji
AU - Saido, Takaomi C.
AU - Sasaki, Erika
AU - Okano, Hideyuki
N1 - Funding Information:
We thank all the laboratory members of H.O., E.S., T.C.S. and N.S. for their generous support and helpful discussions. This study was funded by the “Construction of System for Spread of Primate Model Animals” project, supported by the Strategic Research Program for Brain Sciences and Brain Mapping by Integrated Neurotechnologies for Disease Studies (Brain/MINDS) of the MEXT and the AMED (Grant ID: JP20dm0207001 to H.O., JP17dm0107051 , JP18dm0207065 , JP18dm0207002 to E.S), and “Strategic Exploitation of Neuro-Genetics for Emergence of the Mind” project from the Cabinet Office government of Japan and Scientific Research in Innovative Areas , a MEXT Grant-in-Aid project FY2014–2018 “Brain Protein Aging and Dementia Control” (Grant ID: 26117007 to H.O.), KAKENHI Grant Number 19J12871 , 21J00381 and 21K15112 (to S.Y) from Japan Society for the Promotion of Science (JSPS). S.Y. was also financially supported by RIKEN Junior Research Associate Program . This work was also supported by a Grant-in-Aid for Scientific Research on Innovative Areas "Fluorescence Live imaging" of The Ministry of Education, Culture, Sports, Science, and Technology, Japan.
Publisher Copyright:
© 2022
PY - 2022/12
Y1 - 2022/12
N2 - Alzheimer's disease (AD) is the leading cause of dementia which afflicts tens of millions of people worldwide. Despite many scientific progresses to dissect the AD's molecular basis from studies on various mouse models, it has been suffered from evolutionary species differences. Here, we report generation of a non-human primate (NHP), common marmoset model ubiquitously expressing Amyloid-beta precursor protein (APP) transgenes with the Swedish (KM670/671NL) and Indiana (V717F) mutations. The transgene integration of generated two transgenic marmosets (TG1&TG2) was thoroughly investigated by genomic PCR, whole-genome sequencing, and fluorescence in situ hybridization. By reprogramming, we confirmed the validity of transgene expression in induced neurons in vitro. Moreover, we discovered structural changes in specific brain regions of transgenic marmosets by magnetic resonance imaging analysis, including in the entorhinal cortex and hippocampus. In immunohistochemistry, we detected increased Aβ plaque-like structures in TG1 brain at 7 years old, although evident neuronal loss or glial inflammation was not observed. Thus, this study summarizes our attempt to establish an NHP AD model. Although the transgenesis approach alone seemed not sufficient to fully recapitulate AD in NHPs, it may be beneficial for drug development and further disease modeling by combination with other genetically engineered models and disease-inducing approaches.
AB - Alzheimer's disease (AD) is the leading cause of dementia which afflicts tens of millions of people worldwide. Despite many scientific progresses to dissect the AD's molecular basis from studies on various mouse models, it has been suffered from evolutionary species differences. Here, we report generation of a non-human primate (NHP), common marmoset model ubiquitously expressing Amyloid-beta precursor protein (APP) transgenes with the Swedish (KM670/671NL) and Indiana (V717F) mutations. The transgene integration of generated two transgenic marmosets (TG1&TG2) was thoroughly investigated by genomic PCR, whole-genome sequencing, and fluorescence in situ hybridization. By reprogramming, we confirmed the validity of transgene expression in induced neurons in vitro. Moreover, we discovered structural changes in specific brain regions of transgenic marmosets by magnetic resonance imaging analysis, including in the entorhinal cortex and hippocampus. In immunohistochemistry, we detected increased Aβ plaque-like structures in TG1 brain at 7 years old, although evident neuronal loss or glial inflammation was not observed. Thus, this study summarizes our attempt to establish an NHP AD model. Although the transgenesis approach alone seemed not sufficient to fully recapitulate AD in NHPs, it may be beneficial for drug development and further disease modeling by combination with other genetically engineered models and disease-inducing approaches.
KW - Alzheimer's disease
KW - Common marmoset
KW - Magnetic resonance imaging
KW - Non-human primate
KW - Reprogramming
KW - Transgenesis
KW - Whole-genome sequencing
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U2 - 10.1016/j.neures.2022.08.008
DO - 10.1016/j.neures.2022.08.008
M3 - Article
C2 - 36075457
AN - SCOPUS:85137542860
SN - 0168-0102
VL - 185
SP - 49
EP - 61
JO - Neuroscience Research
JF - Neuroscience Research
ER -